A Phenotype of Atypical Apraxia of Speech in a Family Carrying SQSTM1 Mutation

نویسندگان

  • Claire Boutoleau-Bretonnière
  • Agnès Camuzat
  • Isabelle Le Ber
  • Kawtar Bouya-Ahmed
  • Rita Guerreiro
  • Anne-Laure Deruet
  • Christelle Evrard
  • José Bras
  • Estelle Lamy
  • Elisabeth Auffray-Calvier
  • Amandine Pallardy
  • John Hardy
  • Alexis Brice
  • Pascal Derkinderen
  • Martine Vercelletto
چکیده

SQSTM1 mutations, coding for the p62 protein, were identified as a monogenic cause of Paget disease of bone and of amyotrophic lateral sclerosis. More recently, SQSTM1 mutations were identified in few families with frontotemporal dementia. We report a new family carrying SQSTM1 mutation and presenting with a clinical phenotype of speech apraxia or atypical behavioral disorders, associated with early visuo-contructional deficits. This study further supports the implication of SQSTM1 in frontotemporal dementia, and enlarges the phenotypic spectrum associated with SQSTM1 mutations.

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عنوان ژورنال:

دوره 43  شماره 

صفحات  -

تاریخ انتشار 2015